Abstract

Primary neuroendocrine cancer of the breast (NECB) is an extremely rare
tumor. In 2003, the World Health Organization (WHO) recognized this category with
three well-described subtypes: small cell, large cell, and carcinoid-like carcinoma;
very few peer-review publications based on the WHO definition were encountered
in the literature, and we conducted a literature search to investigate the reported
incidence, diagnosis, prognosis, hormone receptor status, and treatment options for
this rare tumor. Confirming the breast as an origin of neuroendocrine tumor repre-
sents a challenge. The diagnosis is mainly dependent on the exclusion of other extra-
mammary organs based on clinical, radiological, and pathological data.
Primary neuroendocrine carcinoma of the breast is rare - only about 30
cases have been reported in literature. Immunohistochemical examination showing
expression of chromogranin and/or synaptophysin confirms evidence of neuro-
endocrine differentiation. Usually foci of neuroendocrine differentiation can be seen
in breast carcinoma and are reported to be present in about 2-5% of breast cancer
cases. Here, we report a case of breast carcinoma in which most of the areas studied
on the tissue section showed neuroendocrine differentiation.
Primary neuroendocrine carcinoma of the breast is a group that exhibits
morphological features similar to those of neuroendocrine tumors of both the
gastrointestinal tract and the lung.
Case presentation
We report the case of a 50-year-old Caucasian woman with primary small
cell neuroendocrine cancer of the breast, which we characterized with immunohisto-
chemical techniques. A palpable and mobile 3.0 cm tumor was located in the upper-
outer quadrant of her right breast. After pathological confirmation the patient
underwent 8 cycles of chemotherapy, and subsequent radical mastectomy with
axillary lymph node resection were performed. Microscopically, the tumor consisted
predominantly of a diffuse proliferation of small oat cells. The tumor cells were posi-
tive for neuroendocrine markers; 21 of 30 lymph nodes were metastatic.
Local recurrence with multiple lung metastases developed only 5 weeks after
surgery, despite of the transient tumor regression achieved by chemotherapy. This case
reinforces the importance of an early correct diagnosis and the standardization of a
treatment regimen for this very rare tumor.
A correct treatment needs to be chosen.


Keywords

breast cancer, primary small cell neuroendocrine breast cancer, treatment, dissemination